Encyclopedia of Molecular Mechanisms of Disease

2009 Edition
| Editors: Florian Lang

Velo-cardio-facial Syndrome

  • Vimla S. Aggarwal
  • Jelena S. Arnold
  • Anna Blonska*
  • Bernice E. Morrow
Reference work entry
DOI: https://doi.org/10.1007/978-3-540-29676-8_489

Synonyms

VCFS; DiGeorge syndrome; 22q11 deletion syndrome; Shprintzen syndrome; Conotruncal anomaly face syndrome

Definition and Characteristics

VCFS is associated with a wide spectrum of malformations, including 180 clinical findings. The common defects include dysmorphic facies, palate abnormalities, malformed outer ears, chronic otitis media with associated conductive hearing loss, cardiac defects, hypocalcemic hypoparathyroidism, and T-cell mediated immune deficiency. Other features include learning and speech disabilities, as well as a high incidence of psychiatric illness.

Prevalence

The prevalence of the disorder has been estimated at 1 per 4,000 live births.

Genes

About 90% of VCFS patients have a typical 3 Mb deletion on chromosome 22q11, which includes 40 genes. Approximately 8% of the patients have a nested distal deletion endpoint resulting in a 1.5 Mb deletion. There is no difference in the severity in patients with the 1.5 or 3 Mb deletion, suggesting the critical region...

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References

  1. 1.
    Robin NH, Shprintzen RJ (2005) Defining the clinical spectrum of deletion 22q11.2. J Pediatr 47(1):90–96Google Scholar
  2. 2.
    Yamagishi H, Srivastava D (2003) Unraveling the genetic and developmental mysteries of 22q11 deletion syndrome. Trends Mol Med 9(9):383–389PubMedGoogle Scholar
  3. 3.
    Baldini A (2005) Dissecting contiguous gene defects: TBX1. Curr Opin Genet Dev 15(3):279–284PubMedGoogle Scholar
  4. 4.
    Cuneo BF (2001) 22q11.2 deletion syndrome: DiGeorge, velocardiofacial and conotruncal anomaly face syndromes. Curr Opin Pediatr 13(5):465–472PubMedGoogle Scholar
  5. 5.
    Behrman RE, Kliegman RM, Jenson HB (2004) Nelson textbook of pediatrics, 17th edn. Saunders, Philadelphia, PA, pp 210–214, 694, 735, 1181, 1493–1554Google Scholar

Copyright information

© Springer-Verlag GmbH Berlin Heidelberg 2009

Authors and Affiliations

  • Vimla S. Aggarwal
    • 1
  • Jelena S. Arnold
    • 1
  • Anna Blonska*
    • 1
    • 2
  • Bernice E. Morrow
    • 1
  1. 1.Department of Molecular GeneticsAlbert Einstein College of MedicineNew YorkUSA
  2. 2.Department of PathophysiologyWroclaw Medical UniversityWroclawPoland