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Lower abdominal inflammatory myofibroblastic tumor -an unusual presentation- a case report and brief literature review

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Abstract

A 9-year-old girl presented with lethargy, malaise & chest pain. Her blood counts confirmed hypochromic microcytic anemia. She was prescribed iron supplements. Subsequently she was admitted to our hospital with fever and increasing chest and abdominal pain. She was treated with antibiotics, and a diagnosis of “early chest infection” was made. Over the following 2 weeks she failed to improve, and her anemia worsened. She was readmitted, and found to have a mass in her lower abdomen with pressure symptoms on her bowel and bladder. A white-cell scan showed increased uptake in right lower quadrant. An ultrasound and a CT scan confirmed a mass adjacent to her bladder. Needle biopsy showed it to be an unusual localization of an inflammatory myofibroblastic tumor (IMT) of cecum. A presentation with chest pain, fever, anemia and pressure symptoms was highly unusual of a lower abdominal IMT mass. She had a successful excision of the tumor, with resolution of her symptoms.

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Abbreviations

WCC:

white cell count

CRP:

creactive protein

ESR:

erythrocyte sedimentation rate

TSH:

thyroid-stimulating hormone

MCV:

mean corpuscular volume

MCH:

mean corpuscular hemoglobin

MDM2:

mouse double minute 2 homolog

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Authors and Affiliations

  1. Department of Pediatrics, West Cumberland Hospital, Hensingham, Whitehaven, Cumbria, UK

    M. Ilyas Saleem, Mahfud A. Ben-Hamida & T. Mesud Yelbuz

  2. Department of Pediatric Surgery, Royal Victoria Infirmary, Newcastle upon Tyne, UK

    Andrew M. Barrett

  3. Department of Pediatric Gastroenterology, Royal Victoria Infirmary, Newcastle upon Tyne, UK

    Susan K. Bunn

  4. Department of Radiology, West Cumberland Hospital, Whitehaven, Cumbria, UK

    Lawrence Huntley

  5. Department of Cellular Pathology, Royal Victoria Infirmary, Newcastle upon Tyne, UK

    Katrina M. Wood

  6. Department of Pediatric Cardiology and Intensive Care Medicine, Children’s Hospital, Hannover Medical School, Hannover, Germany

    T. Mesud Yelbuz

Authors
  1. M. Ilyas Saleem
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  2. Mahfud A. Ben-Hamida
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  3. Andrew M. Barrett
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  4. Susan K. Bunn
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  5. Lawrence Huntley
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  6. Katrina M. Wood
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  7. T. Mesud Yelbuz
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Correspondence to M. Ilyas Saleem.

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Saleem, M.I., Ben-Hamida, M.A., Barrett, A.M. et al. Lower abdominal inflammatory myofibroblastic tumor -an unusual presentation- a case report and brief literature review. Eur J Pediatr 166, 679–683 (2007). https://doi.org/10.1007/s00431-006-0305-y

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  • DOI: https://doi.org/10.1007/s00431-006-0305-y

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