Summary
An 11-year-old girl experienced several syncopal attacks and her electrocardiogram showed ST depression with exercise. Ostial stenosis of the left coronary artery was disclosed by the coronary angiography. We suspected the coronary involvement was due to Takayasu's arteritis. On operation, aortitis in the ascending aorta involving ostium of the left coronary artery was observed. Therefore Takayasu's arteritis is considered to be one of the causes of sudden death.
This is a preview of subscription content, log in via an institution to check access.
Similar content being viewed by others
References
Nakao K, Ikeda M, Kimata S, Niitani H, Miyahara M, Ishimi Z, Hashiba K, Takeda Y, Ozawa T, Matsushita S, Kuramochi M (1967) Takayasu's arteritis. Clinical report of eighty-four cases and immunological studies of seven cases. Circulation 35: 1141–1155
Lupi HE, Seoane M (1986) Takayasu's arteritis. (Nonspecific aortoarteritis). In: Lande A, Berkman YM, McAllister HA (eds) Aortitis: clinical, pathologic, and radiographic aspects. Raven, New York, pp 173–191
Frovig AG, Locken AC (1951) Syndrome of obliteration of the arterial branches of the aortic arch due to arteritis. Acta Psychiatr Neurol Scand 26: 313–337.
Hiroe M, Sekiguchi M, Take M, Kusakabe K, Shigeta A, Hirosawa K (1985) Long follow-up study in patients with prior myocarditis by radionuclide methods. In: Sekiguchi M, Olsen EGJ, Goodwin JF (eds) Myocarditis and related disorders. Springer-Verlag, New York, pp 199–203
Lee K, Sohn K, Hong C, Kang S, Berg K (1967) Primary arteritis (pulseless disease) in Korean children. Acta Paediatr Scand 56: 526–536
Wiggelinkhuizen J, Cremin BJ (1978) Takayasu arteritis and renovascular hypertension in children. Pediatrics 62: 209–217
Baum J (1986) Takayasu's arteritis in children. In: Lande A, Berkman YM, McAllister HA (eds) Aortitis: clinical, pathologic, and radiographic aspects. Raven, New York, pp205–214
Lupi-Herrerra E, Sanchez-Torres G, Marcushamer J, Mispireta J, Horwitz S, Vela JE (1977) Takayasu's arteritis, Clinical study of 107 cases. Am Heart J 93: 94–103
Cipriano PR, Silverman JF, Perloth MG, Gripp RB, Wexler L (1977) Coronary arterial narrowing in Takayasu's arteritis. Am J Cardiol 39: 744–750
Hata H, Fukuyama M, Okamoto K, Sono J, Okada Y, Miyamoto S, Nishiuchi S, Takemichi K, Shomura T, Yoshizumi M, Inanami H, Yoshida K, Yoshikawa J (1983) A case of aortitis syndrome with bilateral coronary ostial stenosis treated by aorto-coronary bypass grafting. J Jpn Thorac Cardiovasc Surg 31: 1303–1308
Levin DC, Fellows, KE, Abrams HL (1978) Hemodynamically significant primary anomalies of the coronary arteries. Angiographic aspects. Circulation 58: 25–34
Nakanishi T, Takao A, Nakazawa M, Endo M, Niwa K, Takahashi Y (1985) Mucocutaneous lymph node syndrome: clinical, hemodynamic, and angiographic features of coronary obstructive disease. Am J Cardiol 55: 662–668
Schachner L, Dennison Y (1974) Pseudoxanthoma elasticum with severe cardiovascular disease in a child. Am J Dis Child 127: 571–575
Author information
Authors and Affiliations
Rights and permissions
About this article
Cite this article
Seguchi, M., Hino, Y., Aiba, S. et al. Ostial stenosis of the left coronary artery as a sole clinical manifestation of Takayasu's arteritis: A possible cause of unexpected sudden death. Heart Vessels 5, 188–191 (1990). https://doi.org/10.1007/BF02059914
Received:
Revised:
Accepted:
Issue Date:
DOI: https://doi.org/10.1007/BF02059914