Abstract
Persistent singultus is a rare condition, occasionally caused by central nervous system abnormalities.We report a six-year-old girl with daily hiccup events. A polygraphic recording capturing nine singultus episodes showed myoclonia of the diaphragm lasting 104–131 milliseconds, time-locked to bilateral, synchronous, double-spike-and-wave discharges, maximum at frontal contacts. The initial EEG spikes preceded the onset of EMG discharges by 56–64 (median: 59) milliseconds. This is the first description of an epileptic patient with hiccups as the main seizure manifestation. Theelectrophysiological findings suggest a primary generalised form of epilepsy and polysynaptic impulse transmission.
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Hahn, A., Neubauer, B.A. Epileptic diaphragm myoclonus. Epileptic Disord. 14, 418–421 (2012). https://doi.org/10.1684/epd.2012.0540
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DOI: https://doi.org/10.1684/epd.2012.0540