Abstract
Isolated pulmonary involvement in Langerhans Cell Histiocytosis (LCH) is rare in childhood. The authors report a 2-y-old boy who presented with acute history of fever, cough and respiratory distress; later developed pneumothorax; whose CT thorax showed diffuse pulmonary cystic lucencies bilaterally. Lung biopsy confirmed pulmonary LCH with CD1a positivity. Recurrent spontaneous pneumothoraces are common in patients of pulmonary LCH; which necessitates rapid intervention. The authors share their experience of successfully using iodopovidone in pleurodesis for repeated pneumothorax episodes in this child with rare diagnosis of isolated pulmonary LCH.
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SV, SJ, DB, SS worked up, managed and followed the case. BDR played crucial role is diagnosis of case. SV and SJ collected the literature and drafted the manuscript. SV, SJ, DB, BDR and SS edited and approved the final manuscript.
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Verma, S., Jondhale, S., Bansal, D. et al. Iodopovidone Pleurodesis for Isolated Pulmonary Langerhan’s Cell Histiocytosis in a Two Year Old Child. Indian J Pediatr 81, 715–718 (2014). https://doi.org/10.1007/s12098-013-1181-x
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DOI: https://doi.org/10.1007/s12098-013-1181-x