Abstract
Saccular disorders are rare representing only 1.5 % of all laryngeal anomalies. Bifid epiglottis is also an extremely rare congenital anomaly that usually occurs in a syndromic picture in association with other anomalies such as polydactyly, cleft palate and micrognathia, which are seen in Pallister–Hall Syndrome and rarely with other syndromes. We report a case of bilateral saccular cysts and bifid epiglottis in a full term neonate presenting with stridor. The patient’s other congenital anomalies included microretrognathia, short neck, polydactyly of four extremities and hypospadias. The patient underwent staged endoscopic microsurgical marsupialization of both cysts and endoscopic repair of the bifid epiglottis.
This is a preview of subscription content, log in via an institution to check access.
References
Suleyman Y, Sahnur Y, Huseyin Y et al (2010) Stridor in a newborn caused by a congenital laryngocele and bifid epiglottis: a case report and review of the literature. Int J Pediatr Otorhinolaryngol Extra 5:28–31
Ioannis A, Anargyros S, Efthimios K (2011) Surgical and anesthetic considerations of laryngeal saccular cyst: a case report. J Med Case Rep 5:283
Ondrey F, Griffith A, Van Waes C et al (2000) Asymptomatic laryngeal malformations are common in patients with Pallister–Hall syndrome. Am J Med Genet 94:64–67
Flint PW, Haughery BH, Lundo VJ, Niparko JK, Richardson MA, Robbins KT, Thomad JR (2010) Cummings otolaryngology, ch. 62, vol 1, 5th edn. Philadlphia, PA, pp 2535–2541
Kirse DJ, Rees CJ, Celmer AW, Bruegger DE (2006) Endoscopic extended ventriculotomy for congenital saccular cysts of the larynx in infants. Arch Otolaryngol Head Neck Surg 132:724–728
Healy GB, Holt GP, Tucker JA (1976) Bifidepiglottis: anomaly. Laryngoscope 86:1459–1468
Kumar S, Garg S, Sahni JK (2012) Radiofrequency ablation of laryngeal saccular cyst in infants: a series of six cases. Int J Pediatr Otorhinolaryngol 76:667–669
Vasileiadis I, Kapetanakis S, Karakostas E (2012) Internal laryngopyocele as a cause of acute airway obstruction: an extremely rare case and review of the literature. Acta Otorhinolaryngol Ital 32:58–62
Gulia J, Yadav S, Khaowas A et al (2012) Laryngocele: a case report and review of literature. Indian J Otorhinolaryngol 14(1)
Hugo R, Adrián Z, Giselle C (2013) Congenital saccular cyst of the larynx: a rare cause of stridor in neonates and infants. Acta Otorrinolaringol 64:50–54
Silingardi E, Sola N, Santunione A et al (2011) Lateral saccular laryngeal cyst and unexpected asphyxia death. Forensic Sci Int 206(1–3):17–19
Kuo JS, Casey SO et al (1999) Pallister–Hall syndrome: clinical and MR features. AJNR 20:1839–1841
Prowse S, Knight L (2012) Congenital cysts of the infant larynx. Int J Pediatr Otorhinolaryngol 76:708–711
Massoth LJ, Digoy GP (2014) Flexible carbon dioxide laser-assisted endoscopic marsupialization and ablation of a laryngeal saccular cyst in a neonate. Ann Otol Rhinol Laryngol 18
Stroh B, Rimell FL, Mendelson N (1999) Bifid epiglottis. Int J Pediatr Otorhinolaryngol 47(1):81–86
Sturgis EM, Howell LL (1995) Bifid epiglottis syndrome. Int J Pediatr Otorhinolaryngol 33:149–157
Tyler DC (1985) Laryngeal cleft: report of eight patients and a review of the literature. Am J Med Genet 21:61–75
Author information
Authors and Affiliations
Corresponding author
Ethics declarations
Conflict of interest
Rawan Arif, Talal Al-Khatib, Razan Daghistani and Maher Shalbi have declare that they have no conflict of interest.
Human and Animal Rights
This article does not contain any studies with human participants performed by any of the authors and does not contain any studies with animals performed by any of the authors.
Rights and permissions
About this article
Cite this article
Arif, R., Al-Khatib, T., Daghistani, R. et al. Congenital Bilateral Saccular Cysts and Bifid Epiglottis: Presentation and Management. Indian J Otolaryngol Head Neck Surg 68, 118–122 (2016). https://doi.org/10.1007/s12070-015-0960-2
Received:
Accepted:
Published:
Issue Date:
DOI: https://doi.org/10.1007/s12070-015-0960-2