Abstract
The concomitant presence of urethral triplication and caudal duplication is extremely rare with no previous reported cases. We report a case of urethral triplication associated with bladder, sigmoid, and rectum duplication. The patient was initially referred with a history of fecaluria and recurrent urinary tract infection. Physical examination revealed 2 meatal opening on the glans penis. Further investigation revealed three distinct urinary streams, two terminating on the glans penis, and one in the rectum in voiding cystourethrography and retrograde urethrography. Computed tomography demonstrated the bladder divided into two compartments by a complete sagittal septum. The patient was managed by the excision of the rectal ending urethra and removal of the bladder sagittal septum during which, two sigmoidal and rectal segments (the right one filled with fecal) were revealed. The right sigmoid and rectum was resected. The two ventral urethras were kept intact. The postoperative course was uneventful. At his 4 month readmission for colostomy closure, the patient reported good urethral voiding with no complication and recurrence of urinary tract infection and the colostomy was closed with no major complication.
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Acknowledgments
S. Lotfi provided great assistance for final editing the manuscript and we thank Bita Ahmadi (bita_ahmadi77@yahoo.com) for her great efforts for preparing the Schematic picture of this anomaly.
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The authors have no conflict of interest.
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Tourchi, A., Kajbafzadeh, AM., Khakpour, M. et al. Concomitant urethral triplication, bladder, and colon duplication. Int Urol Nephrol 44, 41–44 (2012). https://doi.org/10.1007/s11255-011-9981-2
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DOI: https://doi.org/10.1007/s11255-011-9981-2