Abstract
Purpose
Anchoring vignettes (AVs) are a promising measurement technique to reduce bias in patient-reported outcome (PRO) measures by helping researchers understand differences in how individuals and groups interpret response options. However, little attention has been paid to ensure quality development of AVs, and their performance has not been well assessed in pediatric populations. In this study, we explore the application of a rigorous development process for AVs based upon current standards for PROs, as well as feasibility of AVs when administered to children and adolescents.
Methods
We developed AVs using a rigorous, patient-centered mixed methods process including three phases: (1) development, (2) a pilot study, and (3) a field test. Our proposed process included the generation of a conceptual framework based on the PRO, the Localized Scleroderma Quality of Life Instrument, and numerous vignette-specific considerations. We qualitatively explored readability and comprehension of the AVs (pilot study) and then analyzed ranking patterns within vignette sets (field test).
Results
Four sets of four vignettes were developed. Revisions were suggested at each phase of development. The pilot study demonstrated that children ≥ 10 years had no trouble indicating understanding of the AVs. In the field test, although appropriate rankings of vignettes were generally demonstrated by participants, the percentage of tied rankings was higher than expected in this pediatric group.
Conclusions
This work supports the need for rigorous developmental standards for AVs, as each stage of development suggested revisions. Additionally, AVs showed initial promise for use with pediatric populations; general feasibility and understanding were supported.
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Acknowledgements
The authors would like to thank Rose Cannon, Jennifer Coias, Dafonso Davage, Stephanie Flores-Pollack, Smriti Prasad, and Noelle Teske for their invaluable assistance with this project, as well as Clement Stone for his insight and input into project design. We also would like to acknowledge the vital involvement of the participants and their families, whose experiences drive this work.
Funding
Dr. Torok was supported by The Nancy Taylor Foundation for Chronic Diseases, Inc. (PI: Torok) and NIH-NIAMS (1K23AR059722, PI: Torok). Dr. Jacobe was funded by the James N. Gilliam, M.D. Chair in Dermatology.
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Dr. Zigler declares she has no conflicts of interest. Dr. Jacobe declares she has no conflicts of interest. Dr. Ardalan declares he has no conflicts of interest. Ms. Schollaert declares she has no conflicts of interest. Dr. Lane declares she has no conflicts of interest. Dr. Torok declares she has no conflicts of interest. Dr. Coles declares that she has no conflicts of interest.
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All procedures performed in studies involving human participants were in accordance with the ethical standards of the University of Pittsburgh and UT Southwestern Institutional Review Boards (IRB) and with the 1964 Helsinki declaration and its later amendments or comparable ethical standards. Specifically, the qualitative pilot study occurred at and was approved by the University of Pittsburgh IRB and the quantitative field test occurred at and was approved by both the University of Pittsburgh and the UT Southwestern IRBs.
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Informed consent was obtained from all individual participants included in the study. Adult participant (> 18 yrs old) consent and parental consent/child assent (for minor participants) were obtained in accordance with each institution’s policy.
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Zigler, C.K., Jacobe, H., Ardalan, K. et al. The importance of development standards for anchoring vignettes: an illustrative example from pediatric localized scleroderma quality of life. Qual Life Res 29, 3263–3272 (2020). https://doi.org/10.1007/s11136-020-02575-6
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DOI: https://doi.org/10.1007/s11136-020-02575-6