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Thoracic ossification of ligamentum flavum manifesting holocord syringomyelia: case report


It has been reported that syringomyelia is rarely associated with degenerative spinal disorders, but the case of holocord syringomyelia is never reported. We here present a case of a 59-year-old woman with right shoulder pain, dysesthesia of the right hand, and gait disturbance. Radiographically, examinations of the spine demonstrated holocord syringomyelia with ossification of ligamentum flavum at T2/3 level. Holocord syringomyelia was reduced remarkably after posterior decompression at the T2/3 level, and her symptoms also improved. We speculated that holocord syringomyelia might have developed due to craniospinal pressure dissociation caused by focal compression of dural sac from extradural degenerative change.

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Correspondence to Yoshiaki Takamura.

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Takamura, Y., Takeshima, Y., Matsuoka, R. et al. Thoracic ossification of ligamentum flavum manifesting holocord syringomyelia: case report. Acta Neurochir 160, 881–884 (2018).

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  • Holocord syringomyelia
  • Ossification of ligamentous flavum
  • Thoracic