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Pediatric spinal cord infarct: a rare cause of a rare disorder, (wo)man in barrel syndrome

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Abstract

The “man in barrel syndrome” is a condition which resembles the aspect of patient being constrained in a barrel in which patient presents with bilateral upper limb weakness. It has classically been attributed to supratentorial lesions in watershed zones. We present such a case in a 12-year-old child who presented with bibrachial weakness and was noted to have cervical cord infarct on imaging. Spinal cord infarct is a rare cause of this syndrome, and until now only 20 cases have been described in which cervical cord infarct led to this presentation, all of them being adults. We describe first case report of bibrachial diplegia due to cord infarct in a child. Our case adds to the limited literature of cervical cord ischemia as a cause of “(wo) man in barrel syndrome” and re-iterates the fact that imaging of cervical cord should be considered while evaluating these cases.

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Correspondence to Hima Pendharkar.

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Yadav, N., Pendharkar, H. & Kulkarni, G.B. Pediatric spinal cord infarct: a rare cause of a rare disorder, (wo)man in barrel syndrome. Childs Nerv Syst 37, 2673–2676 (2021). https://doi.org/10.1007/s00381-020-04927-6

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