Abstract
A pregnant woman presented with hereditary hemorrhagic telangiectasia (Osler-Weber-Rendu syndrome) and a single pulmonary arteriovenous malformation (AVM) that had been embolized 5 years previously. Partly due to pregnancy, recanalization of the aneurysm occurred with subsequent hemoptysis. Despite successful therapeutic reembolization of the afferent pulmonary artery, hemoptysis recurred 5 days later. At this time, recanalization of the pulmonary artery was not demonstrated by pulmonary angiography, but a systemic angiogram revealed a bronchial arterial supply to the pulmonary AVM. A systemic supply should always be sought in cases of recurrent hemoptysis after technically successful embolization of the feeding pulmonary artery.
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De Wispelaere, JF., Trigaux, JP., Weynants, P. et al. Systemic supply to a pulmonary arteriovenous malformation: Potential explanation for recurrence. Cardiovasc Intervent Radiol 19, 285–287 (1996). https://doi.org/10.1007/BF02577652
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DOI: https://doi.org/10.1007/BF02577652