Dysphagia

, Volume 2, Issue 1, pp 18–24 | Cite as

Congenital laryngotracheal (LT) cleft: Report of a successful repair in an adult

  • Haskins K. Kashima
  • Bernard R. Marsh
  • Martin W. Donner
  • William J. Ravich
  • Diane Robertson
Article

Abstract

Congenital laryngotracheal (LT) cleft is an uncommon and highly lethal deformity unless corrected early in life. An unusual case of a patient whose cleft was diagnosed and repaired at age 24 years is described. The embryodysgenesis, clinical staging, and the diagnostic and management considerations are reviewed. A limited cleft (Evans Type I) may be more prevalent than is recognized and may be the cause of some presently unaccountable throat symptoms.

Key words

Laryngotracheal cleft Aspiration pneumonia Embryodysgenesis 

Preview

Unable to display preview. Download preview PDF.

Unable to display preview. Download preview PDF.

References

  1. 1.
    Blumberg, J.B., J.K. Stevenson, R.J. Lemire, and E.A. Boyden. 1965. Laryngotrachealesophageal cleft, the embryologic implications: Review of the literature.Surgery 57:559–566.PubMedGoogle Scholar
  2. 2.
    Cohen, S.R. 1975. Cleft larynx. A report of seven cases.Ann. Otol. 84:747–756.Google Scholar
  3. 3.
    Cote, G.B., A. Katsantoni, S. Papadakou-Lagoyanni, C. Costalos, T. Timotheou, A. Skorkalakis, D. Deligeorgis, and S. Pantelakis. 1981. The G-syndrome of ocular hypertelorism and hypospadias.Clin. Genet. 19:473–478.PubMedCrossRefGoogle Scholar
  4. 4.
    Delahunty, J.E., and J. Cherry. 1969. Congenital laryngeal cleft.Ann. Oto. Rhinol. Laryngol. 78:96–106.Google Scholar
  5. 5.
    Evans, J.N.G. 1985. Management of the cleft larynx and tracheoesophageal clefts.Ann. Otol. Rhinol. Laryngol. 94:627–630.PubMedGoogle Scholar
  6. 6.
    Finlay H.V.L. 1949. Familial congenital stridor.Arch. Dis. Child. 24:219–223.PubMedCrossRefGoogle Scholar
  7. 7.
    Jahrsdoerfer, R.A., J.A. Kirchner, and S.U. Thaler. 1967. Cleft larynx.Arch. Otolaryng. 86:108–113.Google Scholar
  8. 8.
    Lim, T.A., S.S. Spanier, and K.I. Kohut, 1979. Laryngeal clefts. A histopathologic study and review.Ann. Otol. 88:837–845.Google Scholar
  9. 9.
    Montgomery, W., and S.A. Smith. 1976. Congenital laryngeal defects in the adult.Ann. Otol. 85:491–497.Google Scholar
  10. 10.
    O'Rahilly, R., and F. Muller. 1984. Respiratory and alimentary relations in staged human embryos. New embryological data and congenital anomalies.Ann. Oto. Rhinol. Laryngol. 5:421–429.Google Scholar
  11. 11.
    Pettersson, G. 1955. Inhibited separation of larynx and the upper part of trachea from oesophagus in a newborn. Report of a case successfully operated upon.Acta. Chir. Scand. 110:250–254.PubMedGoogle Scholar
  12. 12.
    Richter, C.F. Dissertatio medico de infanticido in artis obstetriciae, thesis, Leipzig, 1792 (Cited by Bell DW, et al.).Ann. Otol. Rhinol. Laryngol. 86:616–622.Google Scholar
  13. 13.
    Roth, B., K.G. Rose, G. Benz-Bohm, and H. Gunther. 1983. Laryngo-tracheo-oesophageal cleft. Clinical features, diagnosis and therapy.Eur. J. Pediatr. 140:41–46.CrossRefPubMedGoogle Scholar
  14. 14.
    Shapiro, M.J., and A. Falla. 1966. Congenital posterior cleft larynx. Report of a case.Ann. Otol. Rhinol. Laryngol. 75:961–967.PubMedGoogle Scholar
  15. 15.
    Tucker, J., R. O'Rahilly, and F. Muller. 1985. The human larynx at the end of the embryonic period proper. 2. The laryngeal cavity and the innervation of its lining.Ann. Otol. 94:607–617.Google Scholar
  16. 16.
    Weaver, D.D., C.L. Mapstone, and P. Yu. 1986. The Vater association. Analysis of 46 patients.Am. J. Dis. Child. 140:225–229.PubMedGoogle Scholar
  17. 17.
    Zaw-Tun, H.A. 1982. The tracheo-csophageal septum — fact or fantasy? Origin and development of the respiratory primordium and esophagus.Acta. Anat. 114:1–21.PubMedCrossRefGoogle Scholar

Copyright information

© Springer-Verlag New York Inc 1987

Authors and Affiliations

  • Haskins K. Kashima
    • 1
  • Bernard R. Marsh
    • 1
  • Martin W. Donner
    • 2
  • William J. Ravich
    • 3
  • Diane Robertson
    • 4
  1. 1.Department of Otolaryngology-Head and Neck SurgeryThe Johns Hopkins Medical InstitutionsBaltimoreUSA
  2. 2.Department of The Russell H. Morgan Department of Radiology and Radiological SciencesThe Johns Hopkins Medical InstitutionsBaltimoreUSA
  3. 3.Department of MedicineThe Johns Hopkins Medical InstitutionsBaltimoreUSA
  4. 4.The Johns Hopkins Swallowing CenterThe Johns Hopkins Medical InstitutionsBaltimoreUSA

Personalised recommendations