Summary
An unusual congenital anomaly of the left coronary artery, consisting of ostial stenosis caused by an acute angular origin of the vessel from the aorta in an infant, is presented. This anomaly resulted in progressive myocardial fibrosis and development of left ventricular congestive heart failure. The clinical state mimicked anomalous origin of the left coronary artery from the pulmonary artery.
Similar content being viewed by others
References
Askenazi J, Nadas AS (1975) Anomalous left coronary artery originating from the pulmonary artery: report on 15 cases.Circulation 51:976–987
Byrum CJ, Blackman MS, Schneider B, Sondheimer HM, Kavey RW (1980) Congenital atresia of the left coronary ostium and hypoplasia of the left main coronary artery.Am Heart J 99:354–358
Chaitman BR, Lesperance J, Saltiel J, Bourassa MG (1976) Clinical, angiographic, and hemodynamic findings in patients with anomalous origin of the coronary arteries.Circulation 53:122–131
Cheitlin MD, De Castro CM, McAllister HA (1974) Sudden death as a complication of anomalous left coronary origin from the anterior sinus of Valsalva: a not-so-minor congenital anomaly.Circulation 50:780–787
Freedom RM, Culham JAG, Moes CAF (1974) Anomalies of the coronary arteries. In: Freedom RM, Culham JAG, Moes CAF (eds)Angiocardiography of congenital heart disease 1974. Macmillan, New York, pp 405–421
Liberthson RR, Gang DL, Custer J (1983) Sudden death in an infant with aberrant origin of the right coronary artery from the left sinus of Valsalva of the aorta: case report and review of the literature.Pediatr Cardiol 4:45–48
Mahowald JM, Blieden LC, Coe JI, Edwards JE (1986) Ectopic origin of a coronary artery from the aorta: sudden death in 3 of 23 patients.Chest 89:668–672
Moller JH, Neal WA (1981) Specific cardiopulmonary problems in the neonate and their management. In: Moller JH, Neal WA (eds)Heart disease in infancy 1981. Appleton-Century-Crofts, New York, pp 463–483
Virmani R, Chun PKC, Goldstein RE, Robinowitz M, McAllister HA (1984) Acute takeoffs of the coronary arteries along the aortic wall and congenital coronary ostial valve-like ridges: association with sudden death.J Am Coll Cardiol 3:766–771
Author information
Authors and Affiliations
Rights and permissions
About this article
Cite this article
Tuna, I.C., Bessinger, F.B., Ophoven, J.P. et al. Acute angular origin of left coronary artery from aorta: An unusual cause of left ventricular failure in infancy. Pediatr Cardiol 10, 39–43 (1989). https://doi.org/10.1007/BF02328634
Issue Date:
DOI: https://doi.org/10.1007/BF02328634