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Intestinal and cutaneous hemangiomatosis

Report of a case

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Summary

A case of an 18-year-old patient suffering for more than 5 years from hypochromic anemia of “unknown origin” was described. At the age of 12 years a cutaneous cavernous hemangioma had been removed. The complaints were weakness, pallor, and pica. No signs of G.I. bleeding or abdominal disease appeared.

Because of chronic hypochromic anemia, X-ray finding suggestive of “duodenal tumor,” and presence of occult blood in the feces, as well as positive Cr51 examination, exploratory laparotomy was performed. This operation revealed nearly 50 small, flat, dark-blue hemangiomas scattered along the duodenum, jejunum, ileum, and colon. A few of the tumors were removed and the histologic examination confirmed the diagnosis of cavernous hemangiomas. Continuous iron therapy was administered and in the period of one year after discharge the level of Hgb. varied from 10.0 to 14.0 gm.%.

An association of G.I. tract hemangiomas and similar skin tumors has been recorded in the literature in 19 cases.

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Authors and Affiliations

  1. From Department of Medicine B′, Asaf Harofe Government Hospital, Zerifin, Israel

    W. Pruzanski M.D.

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  1. W. Pruzanski M.D.
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I am indebted to Dr. A. Gefel for helpful critical comments.

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Pruzanski, W. Intestinal and cutaneous hemangiomatosis. Digest Dis Sci 8, 200–205 (1963). https://doi.org/10.1007/BF02232661

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