Abstract
Melorheostosis is a benign, rare, congenital disorder of hyperostosis of one or more bones. In this report, we describe a 5-year-old girl with melorheostosis of the left iliac wing, femur, and tibia who developed severe hypertension secondary to left renal artery stenosis. Numerous soft tissue and vascular anomalies have been reported in patients with melorheostosis. To our knowledge this is the first case where renal artery stenosis has been associated with melorheostosis. Several hypotheses for bone and vascular involvement in melorheostosis are reviewed.
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Leri A, Joanny J (1992) Une affection non décrite des os; hyperostose “encoulée” sur toute la longeur d'un membre ou “mélorhéostose”. Bull Mem Soc Hop Paris 46: 1141–1145
Perlman M (1990) Melorheostosis: a case report and literature review. J Foot Surg 29: 353–356
Hall R (1961) A case of melorheostosis with cutaneous haemangioma and lymphatic vesicles. J Bone Joint Surg [Br] 43B: 335–337
Morris JM, Samilson RL, Corley CL (1963) Melorheostosis Review of the literature and report of an interesting case with a nineteen year follow up. J Bone Joint Surg [Am] 45A: 1191–1206
Applebaum RE, Caniano DA, Sun CC, Azizkhan RA, Queral LA (1986) Synchronous left subclavian and axillary artery aneurysms associated with melorheostosis. Surgery 99: 249–253
Taylor DR (1981) A case of melorheostosis with associated linear cutaneous vascular malformation. Clin Exp Dermatol 6: 47–51
Lewin P, MacLeod SB (1925) Osteosclerosis with distribution suggesting that of the ulnar nerve. An unclassified bone condition. J Bone Joint Surg 7: 969–979
Kessler HB, Recht MP, Dalinka MK (1983) Vascular anomalies in association with osteodystrophies — a spectrum. Skeletal Radiol 10: 95–101
Patrick JH (1969) Melorheostosis associated with arteriovenous aneurysms of the left arm and trunk. J Bone Joint Surg [Br] 51B: 126–129
Walker GF (1964) Mixed sclerosing bone dystrophies. Two case reports. J Bone Joint Surg [Br] 46B: 546–552
Campbell CJ, Papademetriou T, Bonfiglio M (1968) Melorheostosis. A report of the clinical roentgenographic, and pathological findings in 14 cases. J Bone Joint Surg [Am] 50A: 1281–1304
Holliday MA, Barratt TM, Vernier RL (1987) Pediatric nephrology, 2nd edn. Williams and Wilkins, Baltimore, pp 751–753
Stanley JC, Fry WJ (1981) Pediatric renal artery occlusive disease and renovascular hypertension. Arch Surg 116: 669–676
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Iglesias, J.H., Stocks, A.L., Pena, D.R. et al. Renal artery stenosis associated with melorheostosis. Pediatr Nephrol 8, 441–443 (1994). https://doi.org/10.1007/BF00856526
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DOI: https://doi.org/10.1007/BF00856526