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Radiological studies of the cheiro-oral syndrome

Journal of Neurology volume 236, pages 177–181 (1989)Cite this article

Summary

Four cases of the cheiro-oral syndrome are reported, with a review of the clinical symptoms and signs and the neuroradiological methods used to demonstrate the responsible lesion. In each case, angiography, computed tomography (CT) and magnetic resonance imaging (MRI) were performed. The lesion was found in the thalamus in three cases and in the pons in one. Infarction had occurred in three cases and haemorrhage in one. Angiography revealed normal findings in all cases. CT at the onset of the symptoms demonstrated a small haemorrhage in the thalamus in one case but was not helpful in the others, and MRI was required to identify infarction. The anatomical sites responsible for the cheirooral syndrome have been reported to be in the central gyrus, in the thalamus, and in the brain stem. The clinical symptoms and signs reported in the literature and in our four cases are reviewed to evaluate aetiological factors and clinical features according to the three different sites of lesions causing this syndrome.

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Affiliations

  1. Department of Neurological Surgery, Kobe West Municipal Hospital, 4 2-chome Ichibancho, Nagataku, 653, Kobe, Japan

    Y. Kawakami, M. Chikama, T. Tanimoto & Y. Shimamura

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  1. Y. Kawakami
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  2. M. Chikama
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  3. T. Tanimoto
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  4. Y. Shimamura
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Kawakami, Y., Chikama, M., Tanimoto, T. et al. Radiological studies of the cheiro-oral syndrome. J Neurol 236, 177–181 (1989). https://doi.org/10.1007/BF00314338

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  • DOI: https://doi.org/10.1007/BF00314338

Key words

  • Cheiro-oral syndrome
  • Magnetic resonance imaging
  • Computed tomography
  • Central gyrus
  • Thalamus-Brain stem