Clinical Journal of Gastroenterology

, Volume 11, Issue 1, pp 83–86 | Cite as

Spontaneous external biliary fistula arising from an intrahepatic duct

  • Naoto MizumuraEmail author
  • Satoshi Okumura
  • Hiroshi Tsuchihashi
  • Masao Ogawa
  • Masayasu Kawasaki
Case Report


A spontaneous external biliary fistula is most commonly a cholecystocutaneous fistula secondary to acute cholecystitis. A fistula arising from an intrahepatic duct is extremely rare. An 87-year-old man presented with swelling of the epigastric region and right upper quadrant abdomen. He had a history of cholecystectomy and endoscopic sphincterotomy. After antibiotic treatment and surgical opening of both lesions, abdominal computed tomography demonstrated a soft tissue mass cephalad to the umbilicus. We excised the mass, and found it to be associated with a fistula through the linea alba. Fistulography showed an abscess cavity communicating with the intrahepatic duct in segment III. Histopathological examination of the mass showed an abscess without malignancy. The fistula closed spontaneously without laparotomy. In this case, the underlying pathology was considered to be associated with a subcapsular hepatic cyst in segment III.


Biliary fistula Cutaneous fistula Bile ducts Intrahepatic 


Compliance with ethical standards

Conflict of interest

Naoto Mizumura, Satoshi Okumura, Hiroshi Tsuchihashi, Masao Ogawa, and Masayasu Kawasaki declare that they have no conflict of interest.

Human rights

All procedures followed have been performed in accordance with the ethical standards laid down in the 1964 Declaration of Helsinki and its later amendments.

Informed consent

Informed consent was obtained from the patient for inclusion in the study.


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Copyright information

© Japanese Society of Gastroenterology 2017

Authors and Affiliations

  • Naoto Mizumura
    • 1
    Email author
  • Satoshi Okumura
    • 1
  • Hiroshi Tsuchihashi
    • 1
  • Masao Ogawa
    • 1
  • Masayasu Kawasaki
    • 1
  1. 1.Department of SurgeryBellland General HospitalSakaiJapan

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