Infarction of torsed extralobar pulmonary sequestration in adolescence

  • Shin-Ah Son
  • Young Woo Do
  • Young Eun Kim
  • So Mi Lee
  • Deok Heon LeeEmail author
Case Report


Torsion of pulmonary extralobar sequestration is extremely rare in childhood and adolescence, and as it presents with a variety of symptoms ranging from intermittent pain to fever from infarction, differential diagnosis is necessary. Herein, we report a rare case of 13-year-old girl who presented with abdominal pain and fever was diagnosed as infarction of torsed extralobar pulmonary sequestration. Torsed extralobar pulmonary sequestration was removed by thoracoscopic surgery, and the patient remained in good clinical condition.


Pulmonary sequestration Pediatrics Pleural effusion 


Compliance with ethical standards

Conflict of interest

The authors declare that they have no competing interests.

Supplementary material

Video 1. Resection of extralobar pulmonary sequestration via video-assisted thoracoscopic surgery. Extralobar pulmonary sequestration was connected to the descending thoracic aorta by a twisted feeding artery. It was removed after clamping with metal clips and reinforcement using a TachoSil® (MP4 116073 KB)


  1. 1.
    Mendeloff EN. Sequestrations, congenital cystic adenomatoid malformations, and congenital lobar emphysema. Semin Thorac Cardiovasc Surg. 2004;16(3):209–14.CrossRefGoogle Scholar
  2. 2.
    Rosado-de-Christenson ML, Frazier AA, Stocker JT, Templeton PA. From the archives of the AFIP. Extralobar sequestration: radiologic-pathologic correlation. Radiographics. 1993;13(2):425–41.CrossRefGoogle Scholar
  3. 3.
    Karantanas AH. Imaging of pulmonary sequestration. AJR Am J Roentgenol. 1990;155(6):1343.CrossRefGoogle Scholar
  4. 4.
    Kirkendall ES, Guiot AB. Torsed pulmonary sequestration presenting with gastrointestinal manifestations. Clin Pediatr (Phila). 2013;52(10):981–4.CrossRefGoogle Scholar
  5. 5.
    Weinbaum PJ, Bors-Koefoed R, Green KW, Prenatt L. Antenatal sonographic findings in a case of intra-abdominal pulmonary sequestration. Obstet Gynecol. 1989;73(5 Pt 2):860–2.Google Scholar
  6. 6.
    Choe J, Goo HW. Extralobar pulmonary sequestration with hemorrhagic infarction in a child: preoperative imaging diagnosis and pathological correlation. Korean J Radiol. 2015;16(3):662–7.CrossRefGoogle Scholar
  7. 7.
    Lima M, Randi B, Gargano T, Tani G, Pession A, Gregori G. Extralobar pulmonary sequestration presenting with torsion and associated hydrothorax. Eur J Pediatr Surg. 2010;20(3):208–10.CrossRefGoogle Scholar
  8. 8.
    Chen W, Wagner L, Boyd T, Nagarajan R, Dasgupta R. Extralobar pulmonary sequestration presenting with torsion: a case report and review of literature. J Pediatr Surg. 2011;46(10):2025–8.CrossRefGoogle Scholar
  9. 9.
    Shah R, Carver TW, Rivard DC. Torsed pulmonary sequestration presenting as a painful chest mass. Pediatr Radiol. 2010;40(8):1434–5.CrossRefGoogle Scholar
  10. 10.
    Zucker EJ, Tracy DA, Chwals WJ, Solky AC, Lee EY. Paediatric torsed extralobar sequestration containing calcification: imaging findings with pathological correlation. Clin Radiol. 2013;68(1):94–7.CrossRefGoogle Scholar
  11. 11.
    Gawlitza M, Hirsch W, Weisser M, Ritter L, Metzger RP. Torsion of extralobar lung sequestration - lack of contrast medium enhancement could facilitate MRI-based diagnosis. Klin Padiatr. 2014;226(1):38–9.Google Scholar
  12. 12.
    Takeuchi K, Ono A, Yamada A, Toyooka M, Takahashi T, Shigematsu Y, et al. Two adult cases of extralobar pulmonary sequestration: a non-complicated case and a necrotic case with torsion. Pol J Radiol. 2014;79:145–9.CrossRefGoogle Scholar
  13. 13.
    Dishop MK, Kuruvilla S. Primary and metastatic lung tumors in the pediatric population: a review and 25-year experience at a large children’s hospital. Arch Pathol Lab Med. 2008;132(7):1079–103.Google Scholar

Copyright information

© The Japanese Association for Thoracic Surgery 2019

Authors and Affiliations

  • Shin-Ah Son
    • 1
  • Young Woo Do
    • 1
  • Young Eun Kim
    • 1
  • So Mi Lee
    • 2
  • Deok Heon Lee
    • 1
    Email author
  1. 1.Department of Thoracic and Cardiovascular Surgery, School of MedicineKyungpook National University, Kyungpook National University HospitalDaeguSouth Korea
  2. 2.Department of Radiology, School of MedicineKyungpook National University, Kyungpook National University HospitalDaeguSouth Korea

Personalised recommendations