Journal of Inherited Metabolic Disease

, Volume 29, Issue 5, pp 685–685 | Cite as

Persistent increase of plasma butyryl/isobutyrylcarnitine concentrations as marker of SCAD defect and ethylmalonic encephalopathy

  • B. Merinero
  • C. Pérez-Cerdá
  • P. Ruiz Sala
  • I. Ferrer
  • M. J. García
  • M. Martínez Pardo
  • A. Belanger-Quintana
  • J. L. de la Mota
  • E. Martin-Hernández
  • C. Vianey-Saban
  • C. Bischoff
  • N. Gregersen
  • M. Ugarte
Short Report

Summary

High concentrations of butyryl/isobutyrylcarnitine (C4-carnitine) in plasma with increase of ethylmalonic acid (EMA) in urine point to different genetic entities, and further investigations are required to differentiate the possible underlying defect. Here we report three unrelated cases, two neurologically affected and one asymptomatic, with this abnormal metabolite pattern due either to mutations in the ETHE1 gene or to a short-chain acyl-CoA dehydrogenase (SCAD) defect.

Keywords

Glucose Internal Medicine Differential Diagnosis Metabolic Disease Galactose 
These keywords were added by machine and not by the authors. This process is experimental and the keywords may be updated as the learning algorithm improves.

Supplementary material

10545_2006_ESM_342.pdf (262 kb)
Persistent increase of plasma butyryl/isobutyrylcarnitine concentrations as marker of SCAD defect and ethylmalonic encephalopathy

Copyright information

© SSIEM and Springer 2006

Authors and Affiliations

  • B. Merinero
    • 1
  • C. Pérez-Cerdá
    • 1
  • P. Ruiz Sala
    • 1
  • I. Ferrer
    • 1
  • M. J. García
    • 1
  • M. Martínez Pardo
    • 2
  • A. Belanger-Quintana
    • 2
  • J. L. de la Mota
    • 3
  • E. Martin-Hernández
    • 4
  • C. Vianey-Saban
    • 5
  • C. Bischoff
    • 6
  • N. Gregersen
    • 6
  • M. Ugarte
    • 1
  1. 1.Centro de Diagnóstico de Enfermedades Moleculares, Departamento de Biología Molecular, Facultad CienciasUniversidad Autónoma de MadridMadridSpain
  2. 2.Servicio de PediatríaHospital Ramón y CajalMadridSpain
  3. 3.Servicio de PediatríaHospital Materno InfantilMálagaSpain
  4. 4.Servicio de PediatríaHospital Doce de OctubreMadridSpain
  5. 5.Hôpital DebrousseLyonFrance
  6. 6.Aarhus University HospitalAarhusDenmark

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