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Neurological Sciences

, Volume 39, Issue 12, pp 2217–2220 | Cite as

A case of concurrent diurnal and nocturnal paroxysmal dystonia

  • Shenghua Li
  • Xiaomin Pang
  • Lan Chen
  • Chunyong Chen
  • Jingli Liu
Letter to the Editor
  • 37 Downloads

Dear Editor,

Nocturnal paroxysmal dystonia (NPD), first described by Lugaresi and Cirignotta in 1981, is interpreted as a special short form of sleep-related hypermotor epilepsy and is characterized by abnormal dyskinetic movements occur mostly during NREM sleep and with no ictal EEG activity or a diffuse ictal pattern [1, 2, 3]. To the best of our knowledge, there have been very few reports of NPD with attacks occur mainly after awakening from noon sleep. We experienced a peculiar case of NPD presenting with a series of diurnal dystonic episodes and some nocturnal attacks. This case shows that NPD is still a diagnostic challenge for clinicians.

A 41-year-old right-handed Chinese man with a 36-year history of episodes of involuntary movements was admitted to the Department of Neurology, The First Affiliated Hospital of Guangxi Medical University. He was born at term after an uncomplicated pregnancy and delivery, with an uneventful neonatal course. His early developmental milestones...

Notes

Compliance with ethical standards

Conflict of interest

The authors declare that they have no conflict of interest.

Supplementary material

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Copyright information

© Springer-Verlag Italia S.r.l., part of Springer Nature 2018

Authors and Affiliations

  1. 1.Department of NeurologyThe First Affiliated Hospital of Guangxi Medical UniversityNanningChina
  2. 2.Department of Internal MedicineThe Second Affiliated Hospital of Guangxi Medical UniversityNanningChina

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