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Hernia

, Volume 9, Issue 4, pp 378–380 | Cite as

Congenital Spigelian hernia with cryptorchidism: probably a new syndrome

  • V. RaveenthiranEmail author
Case Report

Abstract

Nearly 28% of pediatric Spigelian hernias reported in the literature are associated with ipsilateral cryptorchidism. However, the pathogenetic relationship between the two has not been satisfactorily explained in the past. This paper describes a male neonate born with cryptorchidism and imperforate anus. Anal stenosis following the treatment of imperforate anus had let to the development of multiple hernias including Spigelian hernia on the right side. Surgical exploration revealed the right testis being located within the Spigelian hernia. Based on the sequence of events, it is hypothesized that Spigelian hernia in this case is a sequela of maldescended testis and raised intraabdominal pressure. As this explanation is also applicable to all of the previously reported cases, the author suggests that the combination of Spigelian hernia and ipsilateral cryptorchidism could probably form a hitherto unrecognized new syndrome.

Keywords

Spigelian hernia Lateral ventral hernia Cryptorchidism Undescended testis Testicular embryology Imperforate anus Abdominal wall defects 

References

  1. 1.
    Losanoff JE, Richman BW, Jones JW (2002) Spigelian hernia in a child: case report and review of the literature. Hernia 6:191–193CrossRefPubMedGoogle Scholar
  2. 2.
    Moreno-Egea A, Flores B, Girela E, Martín JG, Aguayo JL, Canteras M (2002) Spigelian hernia: bibliographical study and presentation of a series of 28 patients. Hernia 6:167–170CrossRefPubMedGoogle Scholar
  3. 3.
    Al-Salem AH (2000) Congenital Spigelian hernia and cryptorchidism: cause or coincidence? Pediatr Surg Int 16:433–436CrossRefPubMedGoogle Scholar
  4. 4.
    Pul N, Pul M (1994) Spigelian hernia in children: report of two cases and review of the literature. Yonsei Med J 35:101–104PubMedGoogle Scholar
  5. 5.
    Spangen L (1989) Spigelian hernia. World J Surg 13:573–580CrossRefPubMedGoogle Scholar
  6. 6.
    Levy G, Nagar H, Blachar A, Ben-Sira L, Kessler A (2003) Pre-operative sonographic diagnosis of incarcerated neonatal Spigelian hernia containing the testis. Pediatr Radiol 33:407–409.CrossRefPubMedGoogle Scholar
  7. 7.
    Ostlie DJ, Zerella JT (1998) Undescended testicle associated with Spigelian hernia. J Pediatr Surg 33:1426–1428CrossRefPubMedGoogle Scholar
  8. 8.
    Silberstein PA, Kern IB, Shi ECP (1996) Congenital Spigelian hernia with cryptorchidism. J Pediatr Surg 31:1208–1210CrossRefPubMedGoogle Scholar
  9. 9.
    Graivier L, Bernstein D, RuBane CF (1978) Lateral ventral (Spigelian) hernias in infants and children. Surgery 83:288–290PubMedGoogle Scholar
  10. 10.
    Kaplan LM, Koyle MA, Kaplan GW, Farrer JH, Rajfer J (1986) Association between abdominal wall defect and cryptorchidism. J Urol 136:645–647PubMedGoogle Scholar
  11. 11.
    Redman JF, Brizzolara JP (1985) An unusual case of testicular ectopia. J Urol 133:104PubMedGoogle Scholar

Copyright information

© Springer-Verlag 2005

Authors and Affiliations

  1. 1.Division of Pediatric Surgery, Rajah Muthiah Medical CollegeAnnamalai UniversityAnnamalai NagarIndia
  2. 2.7. Medical Faculty QuartersAnnamalai Nagar 608002India

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