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Myelopathy associated with instability consequent to resection of ossification of anterior longitudinal ligament in DISH

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Abstract

Purpose

The presence of prominent OALL (ossification of anterior longitudinal ligament) in the anterior cervical spine has been implicated as a cause of dysphagia. Surgical resection of the OALL is considered effective for the management of diffuse idiopathic skeletal hyperostosis (DISH)-related dysphagia. Although many reports have been published on DISH-related dysphagia, no cases of postoperative cervical instability have been reported thus far. We present a case in which the patient developed myelopathy associated with instability consequent to resection of OALL in DISH.

Methods

A 62-year-old man presented with progressive dysphagia that persisted for a year. The patient’s symptoms were successfully resolved by resection of OALL. Five years after the surgery, the dysphagia resurfaced and was found to be caused by the regrowth of the OALL. A repeat surgery was performed, and the dysphagia disappeared. Eleven months after the second surgery, he visited the hospital with progressive quadriparesis and pain in the cervical region.

Results

Nine-month follow-up radiologic study revealed cervical instability at the level of C5–6 resulting in myelopathy. The patient underwent decompressive laminectomy and posterior fusion surgery.

Conclusion

Surgical resection of DISH-related dysphagia typically yields excellent outcomes, but our experience in this case highlights the possibility of OALL regrowth and subsequent cervical instability after resection of OALL.

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Acknowledgements

This research was supported by Basic Science Research Program through the National Research Foundation of Korea (NRF) funded by the Ministry of Science, ICT and Future Planning (NRF-2015R1C1A1A01056299).

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Correspondence to Kyoung-Tae Kim.

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Park, MK., Kim, KT., Cho, DC. et al. Myelopathy associated with instability consequent to resection of ossification of anterior longitudinal ligament in DISH. Eur Spine J 27 (Suppl 3), 330–334 (2018). https://doi.org/10.1007/s00586-017-5236-y

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  • DOI: https://doi.org/10.1007/s00586-017-5236-y

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